TY - JOUR
T1 - De novo MGC4607 gene heterozygous missense variants in a child with multiple cerebral cavernous malformations
AU - Mosca, Lorena
AU - Pileggi, Silvana
AU - Avemaria, Francesca
AU - Tarlarini, Claudia
AU - Cigoli, Maria Sole
AU - Capra, Valeria
AU - De Marco, Patrizia
AU - Pavanello, Marco
AU - Marocchi, Alessandro
AU - Penco, Silvana
PY - 2012/7
Y1 - 2012/7
N2 - Cavernous malformations are angiographically occult, low-pressure neurovascular lesions with distinct imaging and clinical characteristics; main clinical manifestations are seizure, focal neurological deficits and epileptic attacks. Here we describe the molecular characterization of an Italian child, a symptomatic patient, affected by multiple cerebral cavernous malformations, without a family history of the disease and harbouring a new MGC4607 gene mutation. We identified two de novo missense variants in exon 6 of the gene both present on the same allele (cis configuration). DNA analysis for KRIT1, and PDCD10 gene variation through direct sequencing and MLPA analysis excluded further mutations. STR multiplex assay, allele-specific analysis and DHPLC analysis were performed for a better genetic characterization. Our findings emphasize the importance of the genetic test in subjects presenting multiple cerebral cavernomas for an adequate counselling, as well as for disease management since early identification of genetic abnormalities enable patients to have their lesions removed before they haemorrhage and cause deficit and/or epilepsy.
AB - Cavernous malformations are angiographically occult, low-pressure neurovascular lesions with distinct imaging and clinical characteristics; main clinical manifestations are seizure, focal neurological deficits and epileptic attacks. Here we describe the molecular characterization of an Italian child, a symptomatic patient, affected by multiple cerebral cavernous malformations, without a family history of the disease and harbouring a new MGC4607 gene mutation. We identified two de novo missense variants in exon 6 of the gene both present on the same allele (cis configuration). DNA analysis for KRIT1, and PDCD10 gene variation through direct sequencing and MLPA analysis excluded further mutations. STR multiplex assay, allele-specific analysis and DHPLC analysis were performed for a better genetic characterization. Our findings emphasize the importance of the genetic test in subjects presenting multiple cerebral cavernomas for an adequate counselling, as well as for disease management since early identification of genetic abnormalities enable patients to have their lesions removed before they haemorrhage and cause deficit and/or epilepsy.
KW - CCM2
KW - Cerebral cavernous malformations
KW - De novo mutation
KW - MGC4607 gene
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U2 - 10.1007/s12031-012-9741-5
DO - 10.1007/s12031-012-9741-5
M3 - Article
C2 - 22415356
AN - SCOPUS:84863878781
SN - 0895-8696
VL - 47
SP - 475
EP - 480
JO - Journal of Molecular Neuroscience
JF - Journal of Molecular Neuroscience
IS - 3
ER -